التفاصيل البيبلوغرافية
| العنوان: |
Progressive retinal vessel malformation in a premature infant with Sturge-Weber syndrome: a case report and a literature review of ocular manifestations in Sturge-Weber syndrome |
| المؤلفون: |
Zhengping Hu, Jian Cao, Eun Young Choi, Yun Li |
| المصدر: |
BMC Ophthalmology, Vol 21, Iss 1, Pp 1-6 (2021) |
| بيانات النشر: |
BMC, 2021. |
| سنة النشر: |
2021 |
| المجموعة: |
LCC:Ophthalmology |
| مصطلحات موضوعية: |
Sturge-weber syndrome, Ocular manifestation, Retinal vessel malformation, Nevus flammeus, Diffuse choroidal hemangioma, Ophthalmology, RE1-994 |
| الوصف: |
Abstract Background Sturge-Weber syndrome is a disorder marked by a distinctive facial capillary malformation, neurological abnormalities, and ocular abnormalities such as glaucoma and choroidal hemangioma. Case presentation We report a case of progressively formed retinal vessel malformation in a premature male infant with Sturge-Weber syndrome and retinopathy of prematurity, after treatment with intravitreal anti-vascular endothelial growth factor (VEGF). The baby was born at 30 weeks gestation with a nevus flammeus involving his left eyelids and maxillary area. On postmenstrual age week 39, he received intravitreal anti-VEGF. Diffuse choroidal hemangioma became evident at 40 weeks, with the classic “tomato catsup fundus” appearance. These clinical findings characterized Sturge-weber syndrome. He presented with posterior retinal vessel tortuosity and vein-to-vein anastomoses at 44 weeks. Conclusion This is a rare case of documented progression of retinal vessel malformations in a patient with Sturge-Weber syndrome and retinopathy of prematurity. |
| نوع الوثيقة: |
article |
| وصف الملف: |
electronic resource |
| اللغة: |
English |
| تدمد: |
1471-2415 |
| Relation: |
https://doaj.org/toc/1471-2415 |
| DOI: |
10.1186/s12886-021-01815-8 |
| URL الوصول: |
https://doaj.org/article/afa4cc442ff14161b913f47f64a576f0 |
| رقم الانضمام: |
edsdoj.fa4cc442ff14161b913f47f64a576f0 |
| قاعدة البيانات: |
Directory of Open Access Journals |
Full Text Finder