Identification of a new heterozygous point mutation in the COL1A2 gene leading to skipping of exon 9 in a patient with joint laxity, hyperextensibility of skin and blue sclerae. Mutations in brief no. 166. Online

التفاصيل البيبلوغرافية
العنوان: Identification of a new heterozygous point mutation in the COL1A2 gene leading to skipping of exon 9 in a patient with joint laxity, hyperextensibility of skin and blue sclerae. Mutations in brief no. 166. Online
المؤلفون: S, Feshchenko, J, Brinckmann, H W, Lehmann, H G, Koch, P K, Müller, S, Kügler
المصدر: Human mutation. 12(2)
سنة النشر: 2000
مصطلحات موضوعية: Joint Instability, Alternative Splicing, Genetic Carrier Screening, Humans, Point Mutation, Ehlers-Danlos Syndrome, Collagen, Exons, Osteogenesis Imperfecta
الوصف: A heterozygous deletion of exon 9 in the COL1A2-mRNA of a patient with symptoms of both the Ehlers-Danlos-Syndrome and the Osteogensis Imperfecta is described. In the genomic DNA of the patient, exon 9 is homozygously present. We identified a novel heterozygous point mutation in the splice donor site of intron 9, leading to a G--A substitution in position +5. This mutation leads to heterozygous skipping of exon 9 in the COL1A2-mRNA of this patient. The deletion results in a shortened (by 18 amino acids) but in frame 12(1) chain, which probably leads to the formation of abberantly processed triple helices.
تدمد: 1059-7794
URL الوصول: https://explore.openaire.eu/search/publication?articleId=pmid________::90708c5e4d96bebd31c3ff24d60bd4a3
https://pubmed.ncbi.nlm.nih.gov/10694924
رقم الانضمام: edsair.pmid..........90708c5e4d96bebd31c3ff24d60bd4a3
قاعدة البيانات: OpenAIRE